Author/Authors :
Liang، Changhu نويسنده Shandong Medical Imaging Research Institute, Affiliated to
Shandong University, Jinan, P. R. China , , Xu، Shifeng نويسنده Department of Surgery, Provincial Hospital, Affiliated to
Shandong University, Jinan, P. R. China , , Zhao، Bin نويسنده , , Ma، Guoyuan نويسنده Department of Thoracic Surgery, Provincial Hospital,
Affiliated to Shandong University, Jinan, P. R. China , , Du، Yinglin نويسنده Shandong Provincial Center for Disease Control and
Prevention, Public Health Institute 72, Jinan, P. R.
China ,
Abstract :
The radiologic features of intralobar pulmonary sequestration
(ILPS) have been describe and include the identification of a feeding
systemic artery with venous drainage through pulmonary veins. Primary
sequestration associated with typical hamartoma signs is really rare and
has been described only once. We describe a patient with ILPS whose
radiographic findings were unusual for two reasons. First, computed
tomography (CT) demonstrated a bulky mass in the pulmonary
sequestration. The size of lesion and histopathology made it an unusual
presentation. Final histology study demonstrated pulmonary hamartoma
with predominantly adipose and cartilage differentiation, which is an
unusual complication originated from ILPS. Another sign also explains
the second unusual feature, intracranial cholesteatoma, occurring
concurrently with ILPS.