Title of article
Renal Involvement in 2 Siblings With Cockayne Syndrome
Author/Authors
Chehida, Amel Ben Department of Pediatrics - La Rabta Hospital, Tunis, Tunisia , Ghali, Narjess Department of Pediatrics - La Rabta Hospital, Tunis, Tunisia , Abdelaziz, Rim Ben Department of Pediatrics - La Rabta Hospital, Tunis, Tunisia , Moussa, Fatma Ben Faculty of Medicine of Tunis - University of Tunis El Manar, Tunis, Tunisia , Tebib, Neji Department of Pediatrics - La Rabta Hospital, Tunis, Tunisia
Pages
3
From page
253
To page
255
Abstract
Renal involvement in Cockayne syndrome is rare and its pathogenesis
is yet unknown. We report herein 2 cases (siblings) with Cockayne
syndrome type A confirmed by biochemical and molecular assays.
The first case was a 13-year-old girl who presented with nephritic
syndrome and a rapidly progressive kidney failure. Her younger
sister, 7 years old, exhibited hypertension, hyperfiltration, and
microalbuminuria. She had hyperreninemia and hyperaldosteronemia
without kidney failure or renal arterial stenosis. Renal biopsy,
performed the older sister, revealed cystic focal segmental
glomerulosclerosis, arteriosclerosis, tubulointerstitial fibrosis,
and tubular atrophy. The different clinical phenotypes in the two
siblings support the absence of an obvious genotype-phenotype
correlation in Cockayne syndrome type A patients. In the older
sister, the particular focal glomerular sclerosis and senile lesions
assume that kidney disease in Cockayne syndrome may be related
to prematurely aging secondary to a defective nucleotide repair.
Keywords
kidney disease , hypertension , focal glomerular sclerosis , Cockayne syndrome
Journal title
Iranian Journal of Kidney Diseases (IJKD)
Serial Year
2017
Record number
2517613
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